{"created":"2023-06-23T12:19:44.292875+00:00","id":10830,"links":{},"metadata":{"_buckets":{"deposit":"865e94e1-cf38-4a00-b802-7b939324ea0a"},"_deposit":{"created_by":21,"id":"10830","owners":[21],"pid":{"revision_id":0,"type":"depid","value":"10830"},"status":"published"},"_oai":{"id":"oai:asahi-u.repo.nii.ac.jp:00010830","sets":["46:348:431"]},"author_link":["4061","3998","14085","14084","14083","14082","8865","8870","4304","4090","4063"],"item_10002_biblio_info_77":{"attribute_name":"書誌情報","attribute_value_mlt":[{"bibliographicIssueDates":{"bibliographicIssueDate":"2019-02","bibliographicIssueDateType":"Issued"},"bibliographicIssueNumber":"3","bibliographicPageEnd":"191","bibliographicPageStart":"187","bibliographicVolumeNumber":"45","bibliographic_titles":[{"bibliographic_title":"岐阜歯科学会雑誌"},{"bibliographic_title":"The Journal of Gifu Dental Society","bibliographic_titleLang":"en"}]}]},"item_10002_description_80":{"attribute_name":"抄録","attribute_value_mlt":[{"subitem_description":"リンパ管腫はリンパ嚢胞を主体とした稀な腫瘤性病変でリンパ管形成異常と考えられている。全身的に発生するが頭頸部や縦隔、腋窩、腹腔、後腹膜内、四肢に好発する。稀に年長児や成人期発症例もある。今回、我々は舌背正中部に発生し経過観察中に拡大したために摘出した先天性リンパ管腫の一例を経験したため、その治療経験に文献的考察を加えて報告する。患者は1歳5か月の男児。2010年2月に舌の腫瘤を主訴に初診来院した。生後5か月時に川崎病で入院した際に、腫瘤を指摘されたが放置していたという。舌背中央部に10×10mmの表面顆粒状のやや赤みのある硬い腫瘤を認めた。超音検査とMRI検査を行った結果、MRIでは舌背粘膜下にT1強調像で中等度信号、T2強調像で高信号を認め、筋層への進展は認めなかった。リンパ管腫と考え、1か月毎の定期的な経過観察を行うこととした。2014年3月来院時、腫瘤は15×12mm へと増大を示したため、患児の両親に説明し全身麻酔下にて切除術を行う方針となった。同年8月に全身麻酔下にて舌背のリンパ管腫切除術施行。腫瘍は筋層や周囲組織からの剥離は容易であり癒着は認めなかった。深部への浸潤も認めず一塊として摘出でき、創部も小さいため創部は縫縮とした。切除標本の病理組織検査では多数の平滑筋層のない管腔形成を認め、免疫組織化学的にリンパ管内皮細胞(D2-40)の裏打ちを認める。血管内皮細胞(CD31)も一部認めるが、リンパ管腫内に点在している毛細血管と思われる。診断は海綿状リンパ管腫であった。術後4年を経過した現在、経過良好で再発等の異常は認めない。","subitem_description_type":"Abstract"}]},"item_10002_description_81":{"attribute_name":"内容記述","attribute_value_mlt":[{"subitem_description":"The rare tumor by which a lymphangioma made the lymphocyst a subject, it's thought lymphangioplasty abnormality by a pathological change. It occurs to the whole body, but it's easy to form in in the head and neck, the mediastinum, the armpit, the abdominal cavity and the film of afterpains and a limb in particular. I also rarely develop the symptoms in an old child and adulthood. Congenital lymphangioma of the tongue is one of abnormal developmental disorder arised in childhood. This tumorgenesis is still unclear and sometimes oral surgeons face with a dilemma to decide removal is required when quick expanding of the lesion is recognized. We report a case of congenital lymphangioma arised in the median dorsum of the tongue levealed expanding growth activity during follow up. One-year and five months-old boy accompanied with Kawasaki disease in the past history, reffered to our hospital and complained swelling of the median dorsum part of the tongue. 10×10mm of reddish hard mass with granular surface was observed. Ultrasonic image showed that the lesion was located between the mucosal epithelium and muscle layer. MRI showed moderate signal of T1 emphasis image and high signal of T2 emphasis image were observed in the lesion. These findings of clinical imaging suggested a kind of vessels tumor and a monthly follow up was scheduled. During four years’ follow-up, the tumor was grown up to 15×12mm and surgically removed under compliance with his parents. Histopathologically, the tumor was composed of prominent number of dilated vessels locataed under the mucosal epithelium and fibrous connective tissue with tiny vessels. These vessels were covered with endothelium lining inside. Immunohistochemically, D2-40 positive but CD31 negative at dilated vessels endothelium showed lymphatic vessels. In contrast, tiny blood vessels around dilated lymphatic vessels were CD31 positive capillary blood vessels. The lesion exhibited immunohistochemical D2-40 positive and hence it was diagnosed as lymphangioma and clinically it was identified as congenital lymphangioma. There was no evidence of recurrence four years after surgery. These findings indicated that this congenital development disorder should be expected surgical remove due to clinical problem.","subitem_description_type":"Other"}]},"item_10002_full_name_75":{"attribute_name":"著者別名","attribute_value_mlt":[{"nameIdentifiers":[{"nameIdentifier":"8870","nameIdentifierScheme":"WEKO"}],"names":[{"name":"YAMAOKA, SHINTARO"}]},{"nameIdentifiers":[{"nameIdentifier":"4304","nameIdentifierScheme":"WEKO"}],"names":[{"name":"OHTA, TAKAHISA"}]},{"nameIdentifiers":[{"nameIdentifier":"14084","nameIdentifierScheme":"WEKO"}],"names":[{"name":"UKAI, AKIRA"}]},{"nameIdentifiers":[{"nameIdentifier":"14085","nameIdentifierScheme":"WEKO"}],"names":[{"name":"MATSUNAGA, RYOKEN"}]},{"affiliations":[{"affiliationNames":[{"affiliationName":"","lang":"ja"}],"nameIdentifiers":[]}],"familyNames":[{"familyName":"山田","familyNameLang":"ja"},{"familyName":"YAMADA","familyNameLang":"en"}],"givenNames":[{"givenName":"和人","givenNameLang":"ja"},{"givenName":"KAZUTO","givenNameLang":"en"}],"nameIdentifiers":[{"nameIdentifier":"4063","nameIdentifierScheme":"WEKO"},{"nameIdentifier":"50240007","nameIdentifierScheme":"e-Rad","nameIdentifierURI":"https://kaken.nii.ac.jp/ja/search/?qm=50240007"}],"names":[{"name":"山田, 和人","nameLang":"ja"},{"name":"YAMADA, KAZUTO","nameLang":"en"}]},{"affiliations":[{"affiliationNames":[{"affiliationName":"","lang":"ja"}],"nameIdentifiers":[]}],"familyNames":[{"familyName":"村松","familyNameLang":"ja"},{"familyName":"MURAMATSU","familyNameLang":"en"}],"givenNames":[{"givenName":"泰徳","givenNameLang":"ja"},{"givenName":"YASUNORI","givenNameLang":"en"}],"nameIdentifiers":[{"nameIdentifier":"4090","nameIdentifierScheme":"WEKO"},{"nameIdentifier":"9000002269874","nameIdentifierScheme":"CiNii ID","nameIdentifierURI":"http://ci.nii.ac.jp/nrid/9000002269874"},{"nameIdentifier":"30247556","nameIdentifierScheme":"e-Rad","nameIdentifierURI":"https://kaken.nii.ac.jp/ja/search/?qm=30247556"}],"names":[{"name":"村松, 泰徳","nameLang":"ja"},{"name":"MURAMATSU, YASUNORI","nameLang":"en"}]},{"affiliations":[{"affiliationNames":[{"affiliationName":"","lang":"ja"}],"nameIdentifiers":[]}],"familyNames":[{"familyName":"住友","familyNameLang":"ja"},{"familyName":"SUMITOMO","familyNameLang":"en"}],"givenNames":[{"givenName":"伸一郎","givenNameLang":"ja"},{"givenName":"SHINICHIRO","givenNameLang":"en"}],"nameIdentifiers":[{"nameIdentifier":"3998","nameIdentifierScheme":"WEKO"},{"nameIdentifier":"1000050216496","nameIdentifierScheme":"CiNii ID","nameIdentifierURI":"http://ci.nii.ac.jp/nrid/1000050216496"},{"nameIdentifier":"50216496","nameIdentifierScheme":"e-Rad","nameIdentifierURI":"https://kaken.nii.ac.jp/ja/search/?qm=50216496"}],"names":[{"name":"住友, 伸一郎","nameLang":"ja"},{"name":"SUMITOMO, SHINICHIRO","nameLang":"en"}]}]},"item_10002_radio_89":{"attribute_name":"フォーマット","attribute_value_mlt":[{"subitem_radio_item":"application/pdf"}]},"item_10002_source_id_82":{"attribute_name":"ISSN","attribute_value_mlt":[{"subitem_source_identifier":"2433-0191","subitem_source_identifier_type":"ISSN"}]},"item_10002_source_id_84":{"attribute_name":"書誌レコードID","attribute_value_mlt":[{"subitem_source_identifier":"AN00053070","subitem_source_identifier_type":"NCID"}]},"item_10002_textarea_76":{"attribute_name":"所属","attribute_value_mlt":[{"subitem_textarea_value":"朝日大学歯学部口腔病態医療学講座口腔外科学分野\n朝日大学病院歯科口腔外科\n朝日大学医科歯科医療センター口腔外科\nDepartment of Oral and Maxillofacial Surgery, Division of Oral Pathogenesis and Disease Control, Asahi University School of Dentistry\nDepartment of Oral and Maxillofacial Surgery, Asahi University Hospital\nDepartment of Oral and Maxillofacial Surgery, Medical and Dental Clinical Center, Asahi University"},{"subitem_textarea_value":"朝日大学歯学部口腔病態医療学講座口腔外科学分野\n朝日大学病院歯科口腔外科\n朝日大学医科歯科医療センター口腔外科\nDepartment of Oral and Maxillofacial Surgery, Division of Oral Pathogenesis and Disease Control, Asahi University School of Dentistry\nDepartment of Oral and Maxillofacial Surgery, Asahi University Hospital\nDepartment of Oral and Maxillofacial Surgery, Medical and Dental Clinical Center, Asahi University"},{"subitem_textarea_value":"福井赤十字病院歯科口腔外科\nDepartment of Dentistry, Oral and Maxillofacial Surgery, Fukui Red Cross Hospital"},{"subitem_textarea_value":"福井赤十字病院歯科口腔外科\nDepartment of Dentistry, Oral and Maxillofacial Surgery, Fukui Red Cross Hospital"},{"subitem_textarea_value":"福井赤十字病院歯科口腔外科\nDepartment of Dentistry, Oral and Maxillofacial Surgery, Fukui Red Cross Hospital"},{"subitem_textarea_value":"朝日大学歯学部口腔病態医療学講座口腔外科学分野\n朝日大学病院歯科口腔外科\n朝日大学医科歯科医療センター口腔外科\nDepartment of Oral and Maxillofacial Surgery, Division of Oral Pathogenesis and Disease Control, Asahi University School of Dentistry\nDepartment of Oral and Maxillofacial Surgery, Asahi University Hospital\nDepartment of Oral and Maxillofacial Surgery, Medical and Dental Clinical Center, Asahi University"},{"subitem_textarea_value":"朝日大学歯学部口腔病態医療学講座口腔外科学分野\n朝日大学病院歯科口腔外科\n朝日大学医科歯科医療センター口腔外科\nDepartment of Oral and Maxillofacial Surgery, Division of Oral Pathogenesis and Disease Control, Asahi University School of Dentistry\nDepartment of Oral and Maxillofacial Surgery, Asahi University Hospital\nDepartment of Oral and Maxillofacial Surgery, Medical and Dental Clinical Center, Asahi University"}]},"item_10002_version_type_95":{"attribute_name":"著者版フラグ","attribute_value_mlt":[{"subitem_version_resource":"http://purl.org/coar/version/c_970fb48d4fbd8a85","subitem_version_type":"VoR"}]},"item_creator":{"attribute_name":"著者","attribute_type":"creator","attribute_value_mlt":[{"creatorAffiliations":[{"affiliationNameIdentifiers":[],"affiliationNames":[{"affiliationName":"","affiliationNameLang":"ja"}]}],"creatorNames":[{"creatorName":"山岡, 真太郎","creatorNameLang":"ja"},{"creatorName":"YAMAOKA, SHINTARO","creatorNameLang":"en"}],"familyNames":[{"familyName":"山岡","familyNameLang":"ja"},{"familyName":"YAMAOKA","familyNameLang":"en"}],"givenNames":[{"givenName":"真太郎","givenNameLang":"ja"},{"givenName":"SHINTARO","givenNameLang":"en"}],"nameIdentifiers":[{"nameIdentifier":"8865","nameIdentifierScheme":"WEKO"},{"nameIdentifier":"9000367026405","nameIdentifierScheme":"CiNii 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YASUNORI","creatorNameLang":"en"}],"familyNames":[{"familyName":"村松","familyNameLang":"ja"},{"familyName":"MURAMATSU","familyNameLang":"en"}],"givenNames":[{"givenName":"泰徳","givenNameLang":"ja"},{"givenName":"YASUNORI","givenNameLang":"en"}],"nameIdentifiers":[{"nameIdentifier":"4090","nameIdentifierScheme":"WEKO"},{"nameIdentifier":"9000002269874","nameIdentifierScheme":"CiNii ID","nameIdentifierURI":"http://ci.nii.ac.jp/nrid/9000002269874"},{"nameIdentifier":"30247556","nameIdentifierScheme":"e-Rad","nameIdentifierURI":"https://kaken.nii.ac.jp/ja/search/?qm=30247556"}]},{"creatorAffiliations":[{"affiliationNameIdentifiers":[],"affiliationNames":[{"affiliationName":"","affiliationNameLang":"ja"}]}],"creatorNames":[{"creatorName":"住友, 伸一郎","creatorNameLang":"ja"},{"creatorName":"SUMITOMO, SHINICHIRO","creatorNameLang":"en"}],"familyNames":[{"familyName":"住友","familyNameLang":"ja"},{"familyName":"SUMITOMO","familyNameLang":"en"}],"givenNames":[{"givenName":"伸一郎","givenNameLang":"ja"},{"givenName":"SHINICHIRO","givenNameLang":"en"}],"nameIdentifiers":[{"nameIdentifier":"3998","nameIdentifierScheme":"WEKO"},{"nameIdentifier":"1000050216496","nameIdentifierScheme":"CiNii ID","nameIdentifierURI":"http://ci.nii.ac.jp/nrid/1000050216496"},{"nameIdentifier":"50216496","nameIdentifierScheme":"e-Rad","nameIdentifierURI":"https://kaken.nii.ac.jp/ja/search/?qm=50216496"}]}]},"item_files":{"attribute_name":"ファイル情報","attribute_type":"file","attribute_value_mlt":[{"accessrole":"open_date","date":[{"dateType":"Available","dateValue":"2019-04-16"}],"displaytype":"detail","filename":"gifushika453_187191_2019.pdf","filesize":[{"value":"7.8 MB"}],"format":"application/pdf","licensetype":"license_11","mimetype":"application/pdf","url":{"label":"gifushika453_187191_2019","url":"https://asahi-u.repo.nii.ac.jp/record/10830/files/gifushika453_187191_2019.pdf"},"version_id":"b46d068f-c5db-440c-a504-0f8d6bc10f22"}]},"item_keyword":{"attribute_name":"キーワード","attribute_value_mlt":[{"subitem_subject":"リンパ管腫","subitem_subject_scheme":"Other"},{"subitem_subject":"先天性疾患","subitem_subject_scheme":"Other"},{"subitem_subject":"舌背正中","subitem_subject_scheme":"Other"},{"subitem_subject":"免疫組織化学","subitem_subject_scheme":"Other"},{"subitem_subject":"小児","subitem_subject_scheme":"Other"},{"subitem_subject":"Lymphangioma","subitem_subject_language":"en","subitem_subject_scheme":"Other"},{"subitem_subject":"Congenital disease","subitem_subject_language":"en","subitem_subject_scheme":"Other"},{"subitem_subject":"Median dorsum tongue","subitem_subject_language":"en","subitem_subject_scheme":"Other"},{"subitem_subject":"immunohistochemistry","subitem_subject_language":"en","subitem_subject_scheme":"Other"},{"subitem_subject":"Childhood","subitem_subject_language":"en","subitem_subject_scheme":"Other"}]},"item_language":{"attribute_name":"言語","attribute_value_mlt":[{"subitem_language":"jpn"}]},"item_resource_type":{"attribute_name":"資源タイプ","attribute_value_mlt":[{"resourcetype":"departmental bulletin paper","resourceuri":"http://purl.org/coar/resource_type/c_6501"}]},"item_title":"舌正中に発症したリンパ管腫の1例","item_titles":{"attribute_name":"タイトル","attribute_value_mlt":[{"subitem_title":"舌正中に発症したリンパ管腫の1例"},{"subitem_title":"A Case of Lymphangioma in the Median Dorsum of Tongue","subitem_title_language":"en"}]},"item_type_id":"10002","owner":"21","path":["431"],"pubdate":{"attribute_name":"公開日","attribute_value":"2019-04-16"},"publish_date":"2019-04-16","publish_status":"0","recid":"10830","relation_version_is_last":true,"title":["舌正中に発症したリンパ管腫の1例"],"weko_creator_id":"21","weko_shared_id":-1},"updated":"2024-01-16T04:55:19.300482+00:00"}